Type presentatie | E-poster |
Titel | Rhinoscleroma: a case report |
Doel | To describe a rare case of rhinoscleroma. |
Methodes | 67-year old male presents with a progressive lesion at the right medial canthus. |
Resultaten | We report a 67-year old Caucasian male presenting with a rapidly progressive right canaliculitis that deteriorated over 1 month towards an infiltrative tumor at the level of the medial canthus. Imaging showed a large extraconal mass on the right orbital side with breaching through the ethmoidal sinuses. A biopsy was performed both transdermally and endoscopically along with local debulking. Pathology disclosed an extensive polyclonal infiltrate with the presence of numerous foamy macrophages and no sign of malignancy. The morphological appearance is not specific but confirmed the diagnosis of rhinoscleroma (Klebsiella Rhinoscleromatis). Long-term systemic treatment for a total duration of 6 months with Ciprofloxacin and Augmentin was given leading to complete regression of the lesion. A right endoscopic dacryocystorhinostomy was performed due to lacrimal canalicular duct scarring leading to residual epiphora. The patient has remained asymptomatic up to 5 years after treatment with imaging showing no evidence of recurrence. |
Conclusie | Rhinoscleroma is a rare chronic granulomatous, slowly progressive infection that affects the respiratory tract structures. This condition is endemic in tropical areas, but extremely rare in Western Europe. Literature describes treatment consisting of a combination of surgery and long-term antibiotics, but describes frequent recurrences. This case report illustrates long-term anatomical outcomes after surgical debulking followed by a 6 month course of antibiotics up to 5 years after treatment. |
Belangenverstrengeling | Nee |
Naam | DESCHUTTERE |
Initialen | C |
Instituut | Dpt of Ophthalmology, Ghent University Hospital |
Stad | Ghent, Belgium |
Naam | NINCLAUS |
Initialen | V |
Instituut | Dpt of Ophthalmology, Ghent University Hospital |
Stad | Ghent, Belgium |